TY - JOUR
T1 - Small Molecule Anion Carriers Correct Abnormal Airway Surface Liquid Properties in Cystic Fibrosis Airway Epithelia
AU - Gianotti, Ambra
AU - Capurro, Valeria
AU - Delpiano, Livia
AU - Mielczarek, Marcin
AU - García-Valverde, María
AU - Carreira-Barral, Israel
AU - Ludovico, Alessandra
AU - Fiore, Michele
AU - Baroni, Debora
AU - Moran, Oscar
AU - Quesada, Roberto
AU - Caci, Emanuela
PY - 2020/2/21
Y1 - 2020/2/21
N2 - Cystic fibrosis (CF) is a genetic disease characterized by the lack of cystic fibrosis transmembrane conductance regulator (CFTR) protein expressed in epithelial cells. The resulting defective chloride and bicarbonate secretion and imbalance of the transepithelial homeostasis lead to abnormal airway surface liquid (ASL) composition and properties. The reduced ASL volume impairs ciliary beating with the consequent accumulation of sticky mucus. This situation prevents the normal mucociliary clearance, favouring the survival and proliferation of bacteria and contributing to the genesis of CF lung disease. Here, we have explored the potential of small molecules capable of facilitating the transmembrane transport of chloride and bicarbonate in order to replace the defective transport activity elicited by CFTR in CF airway epithelia. Primary human bronchial epithelial cells obtained from CF and non-CF patients were differentiated into a mucociliated epithelia in order to assess the effects of our compounds on some key properties of ASL. The treatment of these functional models with non-toxic doses of the synthetic anionophores improved the periciliary fluid composition, reducing the fluid re-absorption, correcting the ASL pH and reducing the viscosity of the mucus, thus representing promising drug candidates for CF therapy.
AB - Cystic fibrosis (CF) is a genetic disease characterized by the lack of cystic fibrosis transmembrane conductance regulator (CFTR) protein expressed in epithelial cells. The resulting defective chloride and bicarbonate secretion and imbalance of the transepithelial homeostasis lead to abnormal airway surface liquid (ASL) composition and properties. The reduced ASL volume impairs ciliary beating with the consequent accumulation of sticky mucus. This situation prevents the normal mucociliary clearance, favouring the survival and proliferation of bacteria and contributing to the genesis of CF lung disease. Here, we have explored the potential of small molecules capable of facilitating the transmembrane transport of chloride and bicarbonate in order to replace the defective transport activity elicited by CFTR in CF airway epithelia. Primary human bronchial epithelial cells obtained from CF and non-CF patients were differentiated into a mucociliated epithelia in order to assess the effects of our compounds on some key properties of ASL. The treatment of these functional models with non-toxic doses of the synthetic anionophores improved the periciliary fluid composition, reducing the fluid re-absorption, correcting the ASL pH and reducing the viscosity of the mucus, thus representing promising drug candidates for CF therapy.
KW - Cell Line
KW - Cystic Fibrosis/drug therapy
KW - Cystic Fibrosis Transmembrane Conductance Regulator/metabolism
KW - Epithelial Cells/metabolism
KW - Humans
KW - Ion Transport/drug effects
KW - Ionophores/chemical synthesis
KW - Mucus/metabolism
KW - Respiratory Mucosa/metabolism
U2 - 10.3390/ijms21041488
DO - 10.3390/ijms21041488
M3 - Article
C2 - 32098269
VL - 21
JO - Int J Mol Sci
JF - Int J Mol Sci
SN - 1422-0067
IS - 4
ER -